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Naderzadeh, A., Attarbashi, A., Pourali, L., Ansari, M., & Abdollahi, A. (2024). Massive aggressive angiomyxoma of ischioanal region with relapse: A case report. International Journal of Reproductive BioMedicine (IJRM), 22(4), 329–334. https://doi.org/10.18502/ijrm.v22i4.16394

https://doi.org/10.18502/ijrm.v22i4.16394

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authors

  • Arezoo Naderzadeh

    Arezoo Naderzadeh

    Endoscopic and Minimally Invasive Surgery Research Center, Mashhad University of Medical Sciences, Mashhad, Iran.
  • Amirhosein Attarbashi

    Amirhosein Attarbashi

    Endoscopic and Minimally Invasive Surgery Research Center, Mashhad University of Medical Sciences, Mashhad, Iran.
  • Leila Pourali

    Leila Pourali

    Supporting the Family and the Youth of Population Research Core, Department of Obstetrics and Gynecology, Faculty of Medicine, Mashhad University of Medical Sciences, Mashhad, Iran.
  • Majid Ansari

    Majid Ansari

    Endoscopic and Minimally Invasive Surgery Research Center, Mashhad University of Medical Sciences, Mashhad, Iran.
  • Abbas Abdollahi

    Abbas Abdollahi

    Endoscopic and Minimally Invasive Surgery Research Center, Mashhad University of Medical Sciences, Mashhad, Iran.

Published Date

  • Jun 8, 2024

Massive aggressive angiomyxoma of ischioanal region with relapse: A case report

International Journal of Reproductive BioMedicine (IJRM) / International Journal of Reproductive BioMedicine (IJRM): Volume 22, Issue No. 4 / Pages 329–334

Abstract

Background: Aggressive angiomyxoma (AA) is a rare and slow-growing tumor in the pelvic and perineal regions that might develop into other perineal structures. It can present variably, ranging from a painless mass to non-specific symptoms such as dyspareunia. Due to the high relapse rate, extensive tumoral resection is reasonably required to prevent recurrences. It is also commonly confused with other conditions such as lipomas, Bartholin’s gland cysts, and hernias.


Case Presentation: A 43-yr-old female diagnosed with AA 10 yr ago was evaluated as a consequence of the tumor recurrence. She presented rare manifestations of a giant and cystic pelvic mass involving pararectal and paravaginal tissue in front of the sacrum.


Conclusion: Although AA is a rare and slow-growing tumor, close observation is recommended due to the high relapse rate. Furthermore, extensive tumoral resection and regular follow-up can reduce morbidity in these patients.


Key words: Vulvar neoplasm, Perineum, Pelvic neoplasms, Recurrence.

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